A Comparative Study of Sociability in Angelman, Cornelia de Lange, Fragile X, Down and Rubinstein Taybi Syndromes and Autism Spectrum Disorder

Jo Moss, Lisa Nelson, Powis Laurie, Jane Waite, Caroline Richards, Chris Oliver

Research output: Contribution to journalArticle

Abstract

Few comparative studies have evaluated the heterogeneity of sociability across a range of neurodevelopmental disorders. The Sociability Questionnaire for People with Intellectual Disability (SQID) was completed by caregivers of individuals with Cornelia de Lange (n = 98), Angelman (n = 66), Fragile X (n = 142), Down (n = 117) and Rubinstein Taybi (n = 88) syndromes and autism spectrum disorder (ASD; n = 107). Between groups and age-band (<12yrs; 12–18yrs; >18yrs) comparisons of SQID scores were conducted. Rates of behaviors indicative of selective mutism were also examined. Fragile X syndrome achieved the lowest SQID scores. Cornelia de Lange, ASD, and Fragile X groups scored significantly lower than Angelman, Down and Rubinstein Taybi groups. Selective mutism characteristics were highest in Cornelia de Lange (40%) followed by Fragile X (17.8%) and ASD (18.2%). Age-band differences were identified in Cornelia de Lange and Down syndrome.
LanguageEnglish
Pages465-486
JournalAmerican Journal on Intellectual and Developmental Disabilities
Volume121
Issue number6
DOIs
Publication statusPublished - 1 Nov 2016

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Rubinstein-Taybi Syndrome
Disabled Persons
Mutism
Intellectual Disability
De Lange Syndrome
Fragile X Syndrome
Down Syndrome
Caregivers
Age Groups
Autism Spectrum Disorder
Surveys and Questionnaires
Sociability
Comparative Study
Syndrome
Autism Spectrum Disorders
Questionnaire

Bibliographical note

©AAIDD. Joanna Moss, Lisa Nelson, Laurie Powis, Jane Waite, Caroline Richards, and Chris Oliver. A Comparative Study of Sociability in Angelman, Cornelia de Lange, Fragile X, Down and Rubinstein Taybi Syndromes and Autism Spectrum Disorder. American Journal on Intellectual and Developmental Disabilities. November 2016, Vol. 121, No. 6, pp. 465-486. https://doi.org/10.1352/1944-7558-121.6.465

Cite this

Moss, Jo ; Nelson, Lisa ; Laurie, Powis ; Waite, Jane ; Richards, Caroline ; Oliver, Chris . / A Comparative Study of Sociability in Angelman, Cornelia de Lange, Fragile X, Down and Rubinstein Taybi Syndromes and Autism Spectrum Disorder. 2016 ; Vol. 121, No. 6. pp. 465-486.
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A Comparative Study of Sociability in Angelman, Cornelia de Lange, Fragile X, Down and Rubinstein Taybi Syndromes and Autism Spectrum Disorder. / Moss, Jo; Nelson, Lisa; Laurie, Powis; Waite, Jane; Richards, Caroline; Oliver, Chris .

Vol. 121, No. 6, 01.11.2016, p. 465-486.

Research output: Contribution to journalArticle

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